Oral Presentation Lorne Infection and Immunity 2020

5-PP-IP5-SPX domain interaction in fungal pathogens - a dangerous liaison (#47)

Sophia Lev 1 2 3 , Desmarini Desmarini 1 3 , Dorothea Fiedler 4 , Julianne Teresa Djordjevic 1 2 3
  1. Centre for Infectious Diseases & Microbiology , Westmead Institute for Medical Research, 176 Hawkesbury Rd, Westmead NSW 2145, Sydney, NSW, Australia
  2. Westmead Clinical School, Faculty of Medicine and Health, University of Sydney, Sydney, NSW, Australia
  3. Marie Bashir Institute, Faculty of Medicine and Health, University of Sydney, Sydney, NSW, Australia
  4. Leibniz-Forschungsinstitut für Molekulare Pharmakologie (FMP), Berlin, Germany

In the human fungal pathogen Cryptococcus neoformans, activation of the phosphate signalling and acquisition (PHO) pathway and production of the inositol pyrophosphate 5-PP-IP5 are essential for fungal dissemination to the host brain and the ensuing fatal meningitis. Whether the PHO pathway and 5-PP-IP5 are connected is unknown. We now demonstrate that 5-PP-IP5 and the PHO pathway intersect at the cyclin-dependent kinase (CDK) inhibitor (CKI) Pho81, to promote activation of the PHO pathway in C. neoformans. This is in contrast to the model yeast, Saccharomyces cerevisiae, where 5-PP-IP5 suppresses PHO pathway activation. Using site-directed mutagenesis of Pho81, Pho81 affinity capture using a custom-made 5-PP-IP5-conjugated resin, Pho81-CDK co-immunoprecipitation and LC-MS, we demonstrate that irrespective of phosphate status, cryptococcal 5-PP-IP5 stabilizes the CKI-CDK complex in vivo by binding to a lysine surface cluster within the SPX domain of CKI Pho81. Disrupting 5-PP-IP5-Pho81 interaction in vivo impairs Pho81-CDK association, leading to defective PHO pathway activation and complete loss of virulence in a mouse infection model. In summary, our study investigating the impact of disrupting a single 5-PP-IP5-SPX domain interaction on fungal virulence has identified a novel role for 5-PP-IP5 in stabilizing the CKI-CDK complex to promote, rather than suppress, PHO pathway activation and highlights evolutionary changes in PHO pathway regulation that promote deadly systemic infection by a fungal pathogen of medical significance.